Logo image
Connexin 26 variants and auditory neuropathy/dys-synchrony among children in schools for the deaf
Journal article   Peer reviewed

Connexin 26 variants and auditory neuropathy/dys-synchrony among children in schools for the deaf

Xing Cheng, Li Li, Shanda Brashears, Thierry Morlet, San San Ng, Charles Berlin, Linda Hood and Bronya Keats
American journal of medical genetics. Part A, v 139(1), pp 13-18
15 Nov 2005
PMID: 16222667

Abstract

Adolescent Child Cochlear Nerve - pathology Connexin 26 Connexin 30 Connexins - genetics Evoked Potentials, Auditory, Brain Stem Hearing Loss - etiology Hearing Loss - genetics Hearing Loss, Sensorineural - genetics Humans Otoacoustic Emissions, Spontaneous Vestibulocochlear Nerve Diseases - complications
Genetic and auditory studies of 731 children with severe-to-profound hearing loss in US schools for the deaf and 46 additional children receiving clinical services for hearing loss ranging from moderate to profound demonstrated that mutations in the connexin 26 (GJB2) and connexin 30 (GJB6) genes explain at least 12% of those with nonsyndromic sensorineural deafness. Otoacoustic emissions (OAEs) testing to detect functional outer hair cells indicated that 76 of the children had emissions and therefore may have (as yet unconfirmed) auditory neuropathy/dys-synchrony (AN/AD). Five of these children with OAEs were GJB2 homozygotes or compound heterozygotes with the genotypes 35delG/35delG, W77X/W77X, 35delG/360delGAG, 35delG/V95M, and V84M/M34T. In particular, unilateral AN/AD was confirmed in a child with moderate hearing loss and the 35delG/V95M genotype. Detecting OAEs in individuals with GJB2 mutations suggests that lack of functional gap junctions as a result of GJB2 mutations does not necessarily destroy all outer hair cell function.

Metrics

Details

UN Sustainable Development Goals (SDGs)

This publication has contributed to the advancement of the following goals:

#3 Good Health and Well-Being

InCites Highlights

Data related to this publication, from InCites Benchmarking & Analytics tool:

Web of Science research areas
Genetics & Heredity
Logo image